Motor Function Measure: Validation of a Short Form for Young Children With Neuromuscular Diseases

被引:69
作者
de Lattre, Capucine [1 ]
Payan, Christine [2 ]
Vuillerot, Carole [1 ]
Rippert, Pascal [3 ]
de Castro, Denis [4 ]
Berard, Carole [1 ]
Poirot, Isabelle [1 ]
机构
[1] Hosp Civils Lyon, Hop Femme Mere Enfant, Pediat Neuromuscular Dis Reference Ctr, Bron, France
[2] Hop La Pitie Salpetriere, AP HP, Dept Clin Pharmacol, Paris, France
[3] Hosp Civils Lyon, Pole Informat Med Evaluat Rech, Lyon, France
[4] Biomed Consulting, Paris, France
来源
ARCHIVES OF PHYSICAL MEDICINE AND REHABILITATION | 2013年 / 94卷 / 11期
关键词
Disability evaluation; Neuromuscular diseases; Rehabilitation; SPINAL MUSCULAR-ATROPHY; OUTCOME MEASURE; SMA-II; SCALE; DYSTROPHY; RELIABILITY;
D O I
10.1016/j.apmr.2013.04.001
中图分类号
R49 [康复医学];
学科分类号
100215 ;
摘要
Objective: To validate a useful version of the Motor Function Measure (MFM) in children with neuromuscular diseases aged <7 years old. Design: Two prospective cohort studies that documented the MFM completion of children aged between 2 and 7 years old. Setting: French-speaking rehabilitation departments from France, Belgium, and Switzerland. Participants: Healthy children (n=194) and children with a neuromuscular disease (n=88). Interventions: Patients were rated by the MFM either once or twice by trained medical professionals, with a delay between the 2 MFMs ranging between 8 and 30 days. Main Outcome Measure: Intra- and interrater reliability of the MFM. Results: The subtests making up the MFM-32, a scale monitoring severity and progression of motor function in patients with a neuromuscular disease in 3 functional domains, were carried out in healthy children aged 2 to 7 years. Twenty items of the MFM-32 were successfully completed by these children and were used to constitute the MFM-20. Principal component analysis of the MFM-20 confirmed the 3 functional domains. Inter- and intrarater reliability of the 3 subscores and total score were high (intraclass correlation coefficient >.90), and discriminant validity was good. Conclusions: The MFM-20 can be used as an outcome measure for assessment of motor function in young children with neuromuscular disease. (C) 2013 by the American Congress of Rehabilitation Medicine
引用
收藏
页码:2218 / 2226
页数:9
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