Nitric oxide inhalation therapy for an infant with persistent pulmonary hypertension caused by misalignment of pulmonary veins with alveolar capillary dysplasia

被引：23

作者：

Kitayama, Y ^{[1
]}

Kamata, S ^{[1
]}

Okuyama, H ^{[1
]}

Usui, N ^{[1
]}

Sawai, T ^{[1
]}

Kobayashi, T ^{[1
]}

Fukui, Y ^{[1
]}

Okada, A ^{[1
]}

机构：

[1] OSAKA UNIV,SCH MED,DEPT PEDIAT SURG,SUITA,OSAKA 565,JAPAN

来源：

JOURNAL OF PEDIATRIC SURGERY | 1997年 / 32卷 / 01期

关键词：

misalignment of pulmonary veins; alveolar capillary dysplasia; pulmonary hypertension; nitric oxide; extracorporeal membrane oxygenation;

D O I：

10.1016/S0022-3468(97)90105-6

中图分类号：

R72 [儿科学];

学科分类号：

100202 ;

摘要：

Misalignment of pulmonary veins with alveolar capillary dysplasia (MPV) has been reported to be a rare cause of persistent pulmonary hypertension of the newborn (PPHN) and to be fatal despite extracorporeal membrane oxygenation (ECMO). A full-term female neonate with PPHN was brought to the hospital for ECMO therapy at 2 days of age. On the 14th day of rife, she was extubated early after the second run of ECMO, and underwent nitric oxide (NO) inhalation therapy in the incubator. She died of catheter-related sepsis on the 61st day of life. After autopsy findings revealed MPV, the longest survival with this disease was documented. NO inhalation therapy in the incubator may provide time for lung transplantation. Copyright (C) 1997 by W.B. Saunders Company

引用

页码：99 / 100

页数：2

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