Autism spectrum disorders and symptoms in children with molecularly confirmed 22q11.2 deletion syndrome

被引:143
作者
Fine, SE
Weissman, A
Gerdes, M
Pinto-Martin, J
Zackai, EH
McDonald-McGinn, DM
Emanuel, BS
机构
[1] Childrens Hosp Philadelphia, Dept Psychol, Philadelphia, PA 19104 USA
[2] Univ Penn, Sch Nursing, Philadelphia, PA 19104 USA
[3] Childrens Hosp Philadelphia, Div Human Genet & Mol Biol, Philadelphia, PA 19104 USA
关键词
22q11.2; Deletion; autism; adaptive behavior;
D O I
10.1007/s10803-005-5036-9
中图分类号
B844 [发展心理学(人类心理学)];
学科分类号
040202 ;
摘要
In this study, we assessed the presence of autism spectrum disorders (ASD) among children with a confirmed 22q11.2 deletion (n = 98). The children's caregivers completed screening measures of ASD behaviors, and for those whose scores indicated significant levels of these behaviors, a standardized diagnostic interview (Autism Diagnostic Interview-Revised; ADI-R) was administered. Results demonstrated that over 20% of children (n = 22) were exhibiting significant levels of autism spectrum symptoms based on the screening measures. Based upon the ADI-R, 14 children qualified for a diagnosis of an ASD, and for 11 of those children a diagnosis of autism was most appropriate. These findings increase our knowledge of developmental disorders associated with the 22q11.2 deletion and point to avenues for future investigation.
引用
收藏
页码:461 / 470
页数:10
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