An autosomal dominant syndrome of renal and anogenital malformations with syndactyly

被引:16
作者
Green, AJ
Sandford, RN
Davison, BCC
机构
[1] ADDENBROOKES NHS TRUST,DEPT CLIN GENET,CAMBRIDGE,ENGLAND
[2] UNIV CAMBRIDGE,DEPT MED GENET,CAMBRIDGE CB2 1TN,ENGLAND
关键词
anal anomalies; syndactyly; renal adysplasia;
D O I
10.1136/jmg.33.7.594
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
We describe a family with autosomal dominant inheritance of anal anomalies, renal tract abnormalities, genital malformations, and syndactyly. These clinical manifestations do not clearly fall into any previously described syndrome. A mother and daughter had almost identical congenital malformations, short stature, and unusual facies. The proband was born with anal stenosis, a rectovaginal fistula, clitoral hypertrophy, a pelvic right kidney, and syndactyly of both feet. Her daughter had the same anal, clitoral, and foot anomalies, a solitary pelvic kidney, and no fistula. This family is likely to represent autosomal dominant inheritance of a new combination of malformations, which may overlap with the Townes-Brocks syndrome, but does not fall into a current diagnostic category.
引用
收藏
页码:594 / 596
页数:3
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