Inherited HFE-unrelated hemochromatosis in Italian families

被引:44
作者
Camaschella, C
Fargion, S
Sampietro, M
Roetto, A
Bosio, S
Garozzo, G
Arosio, C
Piperno, A
机构
[1] Univ Turin, Dipartimento Sci Clin & Biol, Turin, Italy
[2] Univ Milan, Osped Maggiore, IRCCS, Dipartimento Med Interna, Milan, Italy
[3] Azienda Osped Civile MP Arezzo, Serv Med Trasfus, Ragusa, Italy
[4] Univ Milan, Ist Sci Biomed, Azienda Osped S Gerardo, Monza, Italy
关键词
D O I
10.1002/hep.510290509
中图分类号
R57 [消化系及腹部疾病];
学科分类号
摘要
Hemochromatosis (HH) is usually caused by the homozygous state for C282Y mutation in the HFE gene. A minority of iron loaded patients have no mutations in this gene. An infrequent subset shows an early-onset aggressive disorder, denoted juvenile hemochromatosis (JH), which has no linkage to 6p. In this report we describe six patients from three unrelated Italian families, four men and two women, aged 21 to 44 with the typical hemochromatosis phenotype, who are homozygous for the wild type allele at the HFE gene. In two families the disorder is unlinked to 6p; in one family some features of the juvenile form are seen, but linkage to 6p is not excluded. Our results point to genetic forms of hemochromatosis not associated with HFE and raise the problem of whether non-HFE hemochromatosis in Italy is related to the "juvenile" form. They also emphasize the importance of phenotypic as well as genetic diagnosis of HH.
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页码:1563 / 1564
页数:2
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