A novel form of autophagic vacuolar myopathy with late-onset and multiorgan involvement

被引:29
作者
Kaneda, D
Sugie, K
Yamamoto, A
Matsumoto, H
Kato, T
Nonaka, I
Nishino, I
机构
[1] Natl Ctr Neurol & Psychiat, Natl Inst Neurosci, Dept Neuromuscular Res, Tokyo 1878502, Japan
[2] Osaka Red Cross Hosp, Dept Neurol, Osaka, Japan
[3] Natl Ctr Neurol & Psychiat, Natl Ctr Hosp Mental Nervous & Muscular Disorders, Tokyo, Japan
关键词
D O I
10.1212/01.WNL.0000069605.00498.BD
中图分类号
R74 [神经病学与精神病学];
学科分类号
摘要
The authors report a 41-year-old man with a novel form of adult-onset autophagic vacuolar myopathy (AVM) with multiple organ involvement including eyes, heart, liver, lung, kidney, and skeletal muscle. The vacuolar membranes had sarcolemmal features similar to vacuoles in Danon disease, X-linked myopathy with excessive autophagy, and infantile AVM. Lysosome associated membrane protein-2, absent in Danon disease, was present. Defined by distinct clinical features, this disease constitutes the fourth entity in the group of autophagic vacuolar myopathy in which the vacuolar membranes have features of sarcolemma.
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页码:128 / 131
页数:4
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