Is the early development of girls with Rett disorder really normal?

被引:104
作者
Einspieler, C
Kerr, AM
Prechtl, HFR
机构
[1] Med Univ Graz, Inst Physiol, Ctr Physiol Med, A-8010 Graz, Austria
[2] Med Univ Graz, Sect Dev Physiol & Dev Neurol, A-8010 Graz, Austria
[3] Gartnavel Royal Hosp, Acad Ctr, Dept Psychol Med, Glasgow G12 0XH, Lanark, Scotland
关键词
D O I
10.1203/01.PDR.0000155945.94249.0A
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
An apparently normal early development was one of the initial criteria for classical Rett syndrome. However, several investigators considered Rett syndrome to be a developmental disorder manifesting very soon after birth. Videos of 22 Rett cases were assessed carefully for movements, posture, and behavior during the first 6 mo of life. All signs that deviated from the normal standard were recorded meticulously. Special attention was paid to the face, the hands, and body movements. A detailed analysis clearly demonstrated an abnormal quality of general movements (100%), tongue protrusion (62%), postural stiffness (58%), asymmetric eye opening and closing (56%), abnormal finger movements (52%), hand stereotypies (42%), bursts of abnormal facial expressions (42%), bizarre smile (32%), tremor (28%), and stereotyped body movements (15%). Our study is the first to apply specific standardized measures of early spontaneous movements to Rett infants, proving conclusively that the disorder is manifested within the first months of life. Although not necessarily specific, the signs that we have observed will be of value in alerting clinicians to the possibility of the diagnosis at an early stage, when intervention is likely to be most effective.
引用
收藏
页码:696 / 700
页数:5
相关论文
共 26 条
  • [1] Rett syndrome is caused by mutations in X-linked MECP2, encoding methyl-CpG-binding protein 2
    Amir, RE
    Van den Veyver, IB
    Wan, M
    Tran, CQ
    Francke, U
    Zoghbi, HY
    [J]. NATURE GENETICS, 1999, 23 (02) : 185 - 188
  • [2] Rett syndrome neuropathology review 2000
    Armstrong, DD
    [J]. BRAIN & DEVELOPMENT, 2001, 23 : S72 - S76
  • [3] CLINICAL PROFILE OF ANGELMAN SYNDROME AT DIFFERENT AGES
    BUNTINX, IM
    HENNEKAM, RCM
    BROUWER, OF
    STROINK, H
    BEUTEN, J
    MANGELSCHOTS, K
    FRYNS, JP
    [J]. AMERICAN JOURNAL OF MEDICAL GENETICS, 1995, 56 (02): : 176 - 183
  • [4] Nurse recognition of early deviation in development in home videos of infants with Rett disorder
    Burford, B
    Kerr, AM
    Macleod, HA
    [J]. JOURNAL OF INTELLECTUAL DISABILITY RESEARCH, 2003, 47 : 588 - 596
  • [5] Joubert syndrome. Report of 5 cases
    Calleja-Perez, B
    Fernandez-Jaen, A
    Martinez-Bermejo, A
    Pascual-Castroviejo, I
    [J]. REVISTA DE NEUROLOGIA, 1998, 26 (152) : 548 - 550
  • [6] CarmagnatDubois F, 1997, ENCEPHALE, V23, P273
  • [7] The qualitative assessment of general movements in preterm, term and young infants - Review of the methodology
    Einspieler, C
    Prechtl, HFR
    Ferrari, F
    Cioni, G
    Bos, AF
    [J]. EARLY HUMAN DEVELOPMENT, 1997, 50 (01) : 47 - 60
  • [8] The early markers for later dyskinetic cerebral palsy are different from those for spastic cerebral palsy
    Einspieler, C
    Cioni, G
    Paolicelli, PB
    Bos, AF
    Dressler, A
    Ferrari, F
    Roversi, MF
    Prechtl, HFR
    [J]. NEUROPEDIATRICS, 2002, 33 (02) : 73 - 78
  • [9] GIROUX B, 1997, ARCH PEDIATR, V6, P542
  • [10] A PROGRESSIVE SYNDROME OF AUTISM, DEMENTIA, ATAXIA, AND LOSS OF PURPOSEFUL HAND USE IN GIRLS - RETTS SYNDROME - REPORT OF 35 CASES
    HAGBERG, B
    AICARDI, J
    DIAS, K
    RAMOS, O
    [J]. ANNALS OF NEUROLOGY, 1983, 14 (04) : 471 - 479