Elucidating the genetic architecture of familial schizophrenia using rare copy number variant and linkage scans

被引:118
作者
Xu, Bin [1 ,2 ]
Woodroffe, Abigail [4 ]
Rodriguez-Murillo, Laura [2 ]
Roos, J. Louw [6 ]
van Rensburg, Elizabeth J. [7 ]
Abecasis, Goncalo R. [5 ]
Gogos, Joseph A. [1 ,3 ]
Karayiorgou, Maria [2 ]
机构
[1] Columbia Univ, Med Ctr, Dept Physiol & Cellular Biophys, New York, NY 10032 USA
[2] Columbia Univ, Med Ctr, Dept Psychiat, New York, NY 10032 USA
[3] Columbia Univ, Med Ctr, Dept Neurosci, New York, NY 10032 USA
[4] Univ Michigan, Dept Epidemiol, Ann Arbor, MI 48109 USA
[5] Univ Michigan, Dept Biostat, Ann Arbor, MI 48109 USA
[6] Weskoppies Hosp, Dept Psychiat, ZA-0001 Pretoria, South Africa
[7] Univ Pretoria, Dept Genet, ZA-0001 Pretoria, South Africa
关键词
rare mutations; chromosome; 13q34; 1p36; RAPGEF gene family; SPORADIC SCHIZOPHRENIA; SUGGESTIVE EVIDENCE; CHROMOSOME; 13Q32; SUSCEPTIBILITY; POPULATIONS; MARKERS;
D O I
10.1073/pnas.0908584106
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
To elucidate the genetic architecture of familial schizophrenia we combine linkage analysis with studies of fine-level chromosomal variation in families recruited from the Afrikaner population in South Africa. We demonstrate that individually rare inherited copy number variants (CNVs) are more frequent in cases with familial schizophrenia as compared to unaffected controls and affect almost exclusively genic regions. Interestingly, we find that while the prevalence of rare structural variants is similar in familial and sporadic cases, the type of variants is markedly different. In addition, using a high-density linkage scan with a panel of nearly 2,000 markers, we identify a region on chromosome 13q34 that shows genome-wide significant linkage to schizophrenia and show that in the families not linked to this locus, there is evidence for linkage to chromosome 1p36. No causative CNVs were identified in either locus. Overall, our results from approaches designed to detect risk variants with relatively low frequency and high penetrance in a well-defined and relatively homogeneous population, provide strong empirical evidence supporting the notion that multiple genetic variants, including individually rare ones, that affect many different genes contribute to the genetic risk of familial schizophrenia. They also highlight differences in the genetic architecture of the familial and sporadic forms of the disease.
引用
收藏
页码:16746 / 16751
页数:6
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