Outline structure of the human L1 cell adhesion molecule and the sites where mutations cause neurological disorders

被引:116
作者
Bateman, A [1 ]
Jouet, M [1 ]
MacFarlane, J [1 ]
Du, JS [1 ]
Kenwrick, S [1 ]
Chothia, C [1 ]
机构
[1] UNIV CAMBRIDGE, DEPT MED, CAMBRIDGE CB2 2QH, ENGLAND
基金
英国惠康基金;
关键词
fibronectin type III; immunoglobulin superfamily; I set; telokin; X-linked hydrocephalus;
D O I
10.1002/j.1460-2075.1996.tb00993.x
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
The L1 cell adhesion molecule has six domains homologous to members of the immunoglobulin superfamily and five homologous to fibronectin type III domains. We determined the outline structure of the L1 domains by showing that they have, at the key sites that determine conformation, residues similar to those in proteins of known structure. The outline structure describes the relative positions of residues, the major secondary structures and residue solvent accessibility. We use the outline structure to investigate the likely effects of 22 mutations that cause neurological diseases. The mutations are not randomly distributed but cluster in a few regions of the structure. They can be divided into those that act mainly by changing conformation or denaturing their domain and those that alter its surface properties.
引用
收藏
页码:6050 / 6059
页数:10
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