Phenotypic variability in a Spanish family with MNGIE

被引:36
作者
Gamez, J
Ferreiro, C
Accarino, ML
Guarner, L
Tadesse, S
Martí, RA
Andreu, AL
Raguer, N
Cervera, C
Hirano, M
机构
[1] Columbia Univ Coll Phys & Surg, Dept Neurol, New York, NY 10032 USA
[2] Hosp Gral, CIBBM, Barcelona, Spain
[3] Hosp Gral, Dept Neurophysiol, Barcelona, Spain
[4] Hosp Gral, Dept Gastroenterol, Barcelona, Spain
[5] Hosp Gral, Dept Neurol, Barcelona, Spain
关键词
D O I
10.1212/WNL.59.3.455
中图分类号
R74 [神经病学与精神病学];
学科分类号
摘要
Clinical, biochemical, and genetic features of a Spanish family with mitochondrial neurogastrointestinal encephalomyopathy are reported. The proband presented with severe gastrointestinal dysmotility and the affected sister had extraocular muscle weakness. In both affected individuals, biochemical defects of thymidine phosphorylase and a pathogenic G-to-A transition mutation at nucleotide 435 in the thymidine phosphorylase gene were identified. The first thymidine phosphorylase mutation identified in Spain showed phenotypic variability at onset.
引用
收藏
页码:455 / 457
页数:3
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