A familial cryptic subtelomeric deletion 12p with variable phenotypic effect

被引:26
作者
Baker, E
Hinton, L
Callen, DF
Haan, EA
Dobbie, A
Sutherland, GR [1 ]
机构
[1] Womens & Childrens Hosp, Dept Cytogenet & Mol Genet, Ctr Med Genet, Adelaide, SA 5006, Australia
[2] Univ Adelaide, Dept Paediat, Adelaide, SA, Australia
[3] Univ Adelaide, Dept Mol Biosci, Adelaide, SA, Australia
[4] Womens & Childrens Hosp, S Australian Clin Genet Serv, Adelaide, SA 5006, Australia
关键词
chromosome; 12p; fluorescence in situ hybridization; mental retardation; subtelomeric deletion;
D O I
10.1034/j.1399-0004.2002.610305.x
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
A 15-year-old-boy and his mother, both carrying a cryptic deletion within 12p13.33, are described. The proband has a mild phenotype with moderate mental retardation and severe behavioural problems. The mother had some learning difficulties at school. Conventional GTL-banded high-resolution chromosome analysis showed normal karyotypes. Subsequent analysis by fluorescence in situ hybridization using a set of probes specific for the subtelomeric regions of all chromosomes, plus a series of probes at 12p13.33 extending from the 12p telomere, showed that both mother and son carry a 1.65 Mb terminal deletion in this region. There are 10 predicted genes within the deleted region. The unanticipated familial nature of the deletion emphasizes the value of family studies in all cases with subtelomeric abnormalities. It also demonstrates the difficulty in making a clinical diagnosis of individuals with this deletion. To the best of the present authors' knowledge, the proband and his mother are the first patients described with a submicroscopic deletion at 12p13.33.
引用
收藏
页码:198 / 201
页数:4
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