Borate transporter SLC4A11 mutations cause both Harboyan syndrome and non-syndromic corneal endothelial dystrophy

被引:104
作者
Desir, Julie
Moya, Graciela
Reish, Orit
Van Regemorter, Nicole
Deconinck, Hilde
David, Karen L.
Meire, Francoise M.
Abramowicz, Marc J.
机构
[1] ULB, Serv Genet Med, Hop Erasme, Med Genet Lab, B-1070 Brussels, Belgium
[2] Fdn Genos, Buenos Aires, DF, Argentina
[3] Assaf Harofeh Med Ctr, Genet Inst, IL-70300 Zerifin, Israel
[4] Vrije Univ Brussels Hosp, Dept Ophthalmol, Brussels, Belgium
[5] Metropolitan Hosp Ctr, Dept Pediat, Clin Genet Serv, New York, NY 10029 USA
[6] State Univ Ghent Hosp, Dept Ophthalmol, B-9000 Ghent, Belgium
关键词
D O I
10.1136/jmg.2006.046904
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Harboyan syndrome, or corneal dystrophy and perceptive deafness (CDPD), consists of congenital corneal endothelial dystrophy and progressive perceptive deafness, and is transmitted as an autosomal recessive trait. CDPD and autosomal recessive, non-syndromic congenital hereditary endothelial corneal dystrophy (CHED2) both map at overlapping loci at 20p13, and mutations of SLC4A11 were reported recently in CHED2. A genotype study on six families with CDPD and on one family with either CHED or CDPD, from various ethnic backgrounds (in the seventh family, hearing loss could not be assessed because of the proband's young age), is reported here. Novel SLC4A11 mutations were found in all patients. Why some mutations cause hearing loss in addition to corneal dystrophy is presently unclear. These findings extend the implication of the SLC4A11 borate transporter beyond corneal dystrophy to perceptive deafness.
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收藏
页码:322 / 326
页数:5
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