Mutations in RAI1 associated with Smith-Magenis syndrome

被引:242
作者
Slager, RE
Lynn, T
Newton, TL
Vlangos, CN
Finucane, B
Elsea, SH
机构
[1] Michigan State Univ, Grad Program Genet, E Lansing, MI 48823 USA
[2] Michigan State Univ, Dept Zool, E Lansing, MI 48823 USA
[3] Michigan State Univ, Dept Pediat Human Dev, E Lansing, MI 48823 USA
[4] Elwyn Training & Res Inst, Elwyn, PA 19063 USA
关键词
D O I
10.1038/ng1126
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Smith-Magenis syndrome (SMS) is a mental retardation syndrome associated with deletions involving chromosome 17p11.2. Persons with SMS have characteristic behavioral abnormalities, including self-injurious behaviors and sleep disturbance, and distinct craniofacial and skeletal anomalies. We identified dominant frameshift mutations leading to protein truncation in RAI1 in three individuals who have phenotypic features consistent with SMS but do not have 17p11.2 deletions detectable by standard fluorescence in situ hybridization techniques.
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收藏
页码:466 / 468
页数:3
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