C9orf72 hexanucleotide repeat associated with amyotrophic lateral sclerosis and frontotemporal dementia forms RNA G-quadruplexes

被引:255
作者
Fratta, Pietro [1 ,2 ]
Mizielinska, Sarah [1 ]
Nicoll, Andrew J. [1 ,3 ]
Zloh, Mire [4 ]
Fisher, Elizabeth M. C. [1 ,2 ]
Parkinson, Gary [4 ]
Isaacs, Adrian M. [1 ]
机构
[1] UCL Inst Neurol, Dept Neurodegenerat Dis, London WC1N 3BG, England
[2] UCL Inst Neurol, MRC Ctr Neuromuscular Dis, London WC1N 3BG, England
[3] UCL Inst Neurol, MRC Prion Unit, London WC1N 3BG, England
[4] UCL, UCL Sch Pharm, London WC1N 1AX, England
来源
SCIENTIFIC REPORTS | 2012年 / 2卷
基金
英国医学研究理事会;
关键词
MYOTONIC-DYSTROPHY; LOBAR DEGENERATION; EXPANSION; DNA; 5'-UTR; REGION; MODEL; MICE;
D O I
10.1038/srep01016
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
Large expansions of a non-coding GGGGCC-repeat in the first intron of the C9orf72 gene are a common cause of both amyotrophic lateral sclerosis (ALS) and frontotemporal dementia (FTD). G-rich sequences have a propensity for forming highly stable quadruplex structures in both RNA and DNA termed G-quadruplexes. G-quadruplexes have been shown to be involved in a range of processes including telomere stability and RNA transcription, splicing, translation and transport. Here we show using NMR and CD spectroscopy that the C9orf72 hexanucleotide expansion can form a stable G-quadruplex, which has profound implications for disease mechanism in ALS and FTD.
引用
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页数:6
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