Genetic counseling and prenatal diagnosis for the mitochondrial DNA mutations at nucleotide 8993

被引:149
作者
White, SL
Collins, VR
Wolfe, R
Cleary, MA
Shanske, S
DiMauro, S
Dahl, HHM
Thorburn, DR
机构
[1] Royal Childrens Hosp, Murdoch Inst, Melbourne, Vic 3052, Australia
[2] Royal Childrens Hosp, Clin Epidemiol & Biostat Unit, Melbourne, Vic 3052, Australia
[3] Columbia Univ Coll Phys & Surg, Dept Neurol, New York, NY 10032 USA
基金
英国医学研究理事会;
关键词
D O I
10.1086/302488
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Mitochondrial genetics is complicated by heteroplasmy, or mutant load, which may be from 1%-99%, and thus may produce a gene dosage-type effect. Limited data are available for genotype/phenotype correlations in disorders caused by mtDNA mutations; therefore, prenatal diagnosis for mtDNA mutations has been hindered by an inability to predict accurately the clinical severity expected from a mutant load measured in fetal tissue. After reviewing 44 published and 12 unpublished pedigrees, we considered the possibility of prenatal diagnosis for two common mtDNA mutations at nucleotide 8993. We related the severity of symptoms to the mutant load and predicted the clinical outcome of a given mutant load. We also used the available data to generate empirical recurrence risks for genetic counseling, which may be used in conjunction with prenatal diagnosis.
引用
收藏
页码:474 / 482
页数:9
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