Intrathecal Injections in Children With Spinal Muscular Atrophy: Nusinersen Clinical Trial Experience

被引:157
作者
Hache, Manon [1 ]
Swoboda, Kathryn J. [2 ]
Sethna, Navil [3 ]
Farrow-Gillespie, Alan [4 ]
Khandji, Alexander [5 ]
Xia, Shuting [6 ]
Bishop, Kathie M. [6 ]
机构
[1] Columbia Univ, Med Ctr, Div Pediat Anesthesia, 622 W 168th St,BH 440-N, New York, NY 10032 USA
[2] Massachusetts Gen Hosp, Dept Neurol, Boston, MA 02114 USA
[3] Boston Childrens Hosp, Dept Anesthesiol Perioperat & Pain Med, Boston, MA USA
[4] Univ Texas Southwestern Med Sch, Dept Anesthesiol & Pain Management, Dallas, TX USA
[5] Columbia Univ, Dept Radiol, New York, NY 10032 USA
[6] Ionis Pharmaceut Inc, Carlsbad, CA USA
关键词
lumbar puncture; spinal muscular atrophy; antisense oligonucleotide; drug delivery; POSTDURAL PUNCTURE HEADACHE; LUMBAR PUNCTURE; NEEDLE DESIGN; SUCCESS RATE; ANESTHESIA; ULTRASOUND; COMPLICATIONS; BACKACHE; INFANTS; PHASE-1;
D O I
10.1177/0883073815627882
中图分类号
R74 [神经病学与精神病学];
学科分类号
摘要
Nusinersen (ISIS-SMNRx or ISIS 396443) is an antisense oligonucleotide drug administered intrathecally to treat spinal muscular atrophy. We summarize lumbar puncture experience in children with spinal muscular atrophy during a phase 1 open-label study of nusinersen and its extension. During the studies, 73 lumbar punctures were performed in 28 patients 2 to 14 years of age with type 2/3 spinal muscular atrophy. No complications occurred in 50 (68%) lumbar punctures; in 23 (32%) procedures, adverse events were attributed to lumbar puncture. Most common adverse events were headache (n = 9), back pain (n = 9), and post-lumbar puncture syndrome (n = 8). In a subgroup analysis, adverse events were more frequent in older children, children with type 3 spinal muscular atrophy, and with a 21- or 22-gauge needle compared to a 24-gauge needle or smaller. Lumbar punctures were successfully performed in children with spinal muscular atrophy; lumbar puncture-related adverse event frequency was similar to that previously reported in children.
引用
收藏
页码:899 / 906
页数:8
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