Periodic paralysis: understanding channelopathies.

被引:35
作者
Lehmann-Horn F. [1 ]
Jurkat-Rott K. [1 ]
Rüdel R. [1 ]
机构
[1] Department of Physiology, Ulm University, Albert-Einstein-Allee II, Ulm
关键词
Sodium Channel; Channel Mutation; Periodic Paralysis; Slow Inactivation; Hypokalemic Periodic Paralysis;
D O I
10.1007/s11910-002-0055-9
中图分类号
学科分类号
摘要
Familial periodic paralyses are typical channelopathies (i.e., caused by functional disturbances of ion channel proteins). The episodes of flaccid muscle weakness observed in these disorders are due to underexcitability of sarcolemma leading to a silent electromyogram and the lack of action potentials even upon electrical stimulation. Interictally, ion channel malfunction is well compensated, so that special exogenous or endogenous triggers are required to produce symptoms in the patients. An especially obvious trigger is the level of serum potassium (K+), the ion responsible for resting membrane potential and degree of excitability. The clinical symptoms can be caused by mutations in genes coding for ion channels that mediate different functions for maintaining the resting potential or propagating the action potential, the basis of excitability. The phenotype is determined by the type of functional defect brought about by the mutations, rather than the channel effected, because the contrary phenotypes hyperkalemic periodic paralysis (HyperPP) and hypokalemic periodic paralysis (HypoPP) may be caused by point mutations in the same gene. Still, the common mechanism for inexcitability in all known episodic-weakness phenotypes is a long-lasting depolarization that inactivates sodium ion (Na+) channels, initiating the action potential.
引用
收藏
页码:61 / 69
页数:8
相关论文
共 124 条
[41]  
Sternberg D(1993)Functional expression of sodium channel mutations identified in families with periodic paralysis Neuron 10 317-326
[42]  
Maisonobe T(1999)A novel syndrome of episodic muscle weakness maps to Xp22.3 Am J Hum Genet 65 1104-1113
[43]  
Jurkat-Rott K(undefined)undefined undefined undefined undefined-undefined
[44]  
Ptécek LJ(undefined)undefined undefined undefined undefined-undefined
[45]  
George AL(undefined)undefined undefined undefined undefined-undefined
[46]  
Griggs RC(undefined)undefined undefined undefined undefined-undefined
[47]  
Rojas CV(undefined)undefined undefined undefined undefined-undefined
[48]  
Wang J(undefined)undefined undefined undefined undefined-undefined
[49]  
Schwartz L(undefined)undefined undefined undefined undefined-undefined
[50]  
McClatchey AI(undefined)undefined undefined undefined undefined-undefined